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  <front>
    <journal-meta>
      <journal-id journal-id-type="publisher-id">abc</journal-id>
      <journal-title-group>
        <journal-title>Arquivos Brasileiros de Cardiologia</journal-title>
        <abbrev-journal-title abbrev-type="publisher">Arq. Bras. Cardiol.</abbrev-journal-title>
      </journal-title-group>
      <issn pub-type="ppub">0066-782X</issn>
      <issn pub-type="epub">1678-4170</issn>
      <publisher>
        <publisher-name>Sociedade Brasileira de Cardiologia - SBC</publisher-name>
        <publisher-loc>S&#227;o Paulo, SP, Brazil</publisher-loc>
      </publisher>
    </journal-meta>
    <article-meta>
      <article-id pub-id-type="publisher-id" specific-use="scielo-v3">C4qPdCBc3T89g8p9GDv8txP</article-id>
      <article-id pub-id-type="other">00025</article-id>
      <article-id pub-id-type="publisher-id" specific-use="scielo-v2">S0066-782X2007000400025</article-id>
      <article-id pub-id-type="publisher-id" specific-use="scielo-v1">S0066-782X(07)08800425</article-id>
      <article-id pub-id-type="doi">10.1590/S0066-782X2007000400025</article-id>
      <article-categories>
        <subj-group subj-group-type="heading">
          <subject>Relato de Caso</subject>
        </subj-group>
      </article-categories>
      <title-group>
        <article-title>Endocardite em v&#225;lvula de Eust&#225;quio</article-title>
      </title-group>
      <contrib-group>
        <contrib contrib-type="author">
          <name>
            <surname>Veiga</surname>
            <given-names>Viviane Cordeiro</given-names>
          </name>
          <xref ref-type="aff" rid="aff01"/>
        </contrib>
        <contrib contrib-type="author">
          <name>
            <surname>Molinari</surname>
            <given-names>Ana Cristina Carlo Magno</given-names>
          </name>
          <xref ref-type="aff" rid="aff01"/>
        </contrib>
        <contrib contrib-type="author">
          <name>
            <surname>Farias</surname>
            <given-names>C&#237;ntia Mara</given-names>
          </name>
          <xref ref-type="aff" rid="aff01"/>
        </contrib>
        <contrib contrib-type="author">
          <name>
            <surname>Silva Junior</surname>
            <given-names>Amilton</given-names>
          </name>
          <xref ref-type="aff" rid="aff01"/>
        </contrib>
        <contrib contrib-type="author">
          <name>
            <surname>Marum</surname>
            <given-names>Elias C&#233;sar Hauy</given-names>
          </name>
          <xref ref-type="aff" rid="aff01"/>
        </contrib>
        <contrib contrib-type="author">
          <name>
            <surname>Rojas</surname>
            <given-names>Salom&#243;n Ordinola</given-names>
          </name>
          <xref ref-type="aff" rid="aff01"/>
        </contrib>
        <contrib contrib-type="author">
          <name>
            <surname>Patr&#237;cio</surname>
            <given-names>Marcelo Luiz</given-names>
          </name>
          <xref ref-type="aff" rid="aff01"/>
        </contrib>
        <contrib contrib-type="author">
          <name>
            <surname>Abensur</surname>
            <given-names>Henry</given-names>
          </name>
          <xref ref-type="aff" rid="aff01"/>
        </contrib>
      </contrib-group>
      <aff id="aff01">
        <addr-line>
          <named-content content-type="city">S&#227;o Paulo</named-content>
          <named-content content-type="state">SP</named-content>
        </addr-line>
        <institution content-type="orgname">Real e Benem&#233;rita Associa&#231;&#227;o Portuguesa de Benefic&#234;ncia</institution>
      </aff>
      <pub-date date-type="collection" publication-format="electronic">
        <month>04</month>
        <year>2007</year>
      </pub-date>
      <volume>88</volume>
      <issue>4</issue>
      <fpage>e79</fpage>
      <lpage>e80</lpage>
      <history>
        <date date-type="accepted">
          <day>14</day>
          <month>09</month>
          <year>2006</year>
        </date>
        <date date-type="rev-recd">
          <day>16</day>
          <month>08</month>
          <year>2006</year>
        </date>
        <date date-type="received">
          <day>19</day>
          <month>05</month>
          <year>2006</year>
        </date>
      </history>
      <permissions>
        <license license-type="open-access" xlink:href="http://creativecommons.org/licenses/by-nc/4.0/" xml:lang="en">
          <license-p>This work is licensed under a Creative Commons Attribution-NonCommercial 4.0 International License.</license-p>
        </license>
      </permissions>
      <abstract>
        <p>A endocardite em v&#225;lvula de Eust&#225;quio &#233; uma condi&#231;&#227;o rara, que ocorre geralmente em usu&#225;rios de drogas injet&#225;veis e em portadores de marcapasso ou cateter venoso central. Apresentamos um caso de paciente que, em p&#243;s-operat&#243;rio de cirurgia de revasculariza&#231;&#227;o do mioc&#225;rdio com circula&#231;&#227;o extracorp&#243;rea, apresentou endocardite em v&#225;lvula de Eust&#225;quio diagnosticada pela ecocardiografia, sendo identificada Klebsiella pneumoniae &#224; hemocultura. O paciente foi tratado com antibioticoterapia apropriada, apresentando resolu&#231;&#227;o do quadro em quatro semanas.</p>
      </abstract>
      <kwd-group xml:lang="pt" kwd-group-type="author-generated">
        <kwd>Endocardite</kwd>
        <kwd>v&#225;lvula de Eust&#225;quio</kwd>
        <kwd>valvas card&#237;acas</kwd>
      </kwd-group>
      <pub-date publication-format="electronic" date-type="pub">
        <day>24</day>
        <month>05</month>
        <year>2007</year>
      </pub-date>
    </article-meta>
  </front>
  <body>
    <p>
      <bold>RELATO DE CASO</bold>
    </p>
    <p>
      <bold>Endocardite em v&#225;lvula de Eust&#225;quio</bold>
    </p>
    <p>
      <bold>Viviane Cordeiro Veiga; Ana Cristina Carlo Magno Molinari; C&#237;ntia Mara Farias; Amilton Silva Junior; Elias C&#233;sar Hauy Marum; Salom&#243;n Ordinola Rojas; Marcelo Luiz Patr&#237;cio; Henry Abensur</bold>
    </p>
    <p>Real e Benem&#233;rita Associa&#231;&#227;o Portuguesa de Benefic&#234;ncia &#150; S&#227;o Paulo, SP</p>
    <p>
      <xref ref-type="corresp" rid="back">Correspond&#234;ncia</xref>
    </p>
    <p>
      <bold>RESUMO</bold>
    </p>
    <p>A endocardite em v&#225;lvula de Eust&#225;quio &#233; uma condi&#231;&#227;o rara, que ocorre geralmente em usu&#225;rios de drogas injet&#225;veis e em portadores de marcapasso ou cateter venoso central. Apresentamos um caso de paciente que, em p&#243;s-operat&#243;rio de cirurgia de revasculariza&#231;&#227;o do mioc&#225;rdio com circula&#231;&#227;o extracorp&#243;rea, apresentou endocardite em v&#225;lvula de Eust&#225;quio diagnosticada pela ecocardiografia, sendo identificada <italic>Klebsiella pneumoniae</italic> &#224; hemocultura. O paciente foi tratado com antibioticoterapia apropriada, apresentando resolu&#231;&#227;o do quadro em quatro semanas.</p>
    <p><bold>Palavras-chave:</bold> Endocardite, v&#225;lvula de Eust&#225;quio, valvas card&#237;acas.</p>
    <p>
      <bold>Introdu&#231;&#227;o</bold>
    </p>
    <p>A endocardite em v&#225;lvula de Eust&#225;quio &#233; uma condi&#231;&#227;o rara, que ocorre geralmente em usu&#225;rios de drogas injet&#225;veis e em portadores de marcapasso ou cateter venoso central<sup>1,2</sup>.</p>
    <p>Na circula&#231;&#227;o fetal, a v&#225;lvula de Eust&#225;quio desvia o sangue da veia cava inferior para o &#225;trio esquerdo atrav&#233;s do forame oval.</p>
    <p>O objetivo deste trabalho &#233; apresentar o relato de um caso de endocardite em v&#225;lvula de Eust&#225;quio no p&#243;s-operat&#243;rio de cirurgia card&#237;aca.</p>
    <p>
      <bold>Relato do Caso</bold>
    </p>
    <p>Paciente de 45 anos, do sexo masculino, com diagn&#243;stico de insufici&#234;ncia coronariana, submetido a cirurgia de revasculariza&#231;&#227;o do mioc&#225;rdio, com anastomose da art&#233;ria tor&#225;cica interna direita para a art&#233;ria coron&#225;ria direita e da art&#233;ria radial esquerda para o ramo marginal esquerdo, com circula&#231;&#227;o extracorp&#243;rea, sem intercorr&#234;ncias, tendo como procedimentos invasivos durante a realiza&#231;&#227;o da cirurgia a cateteriza&#231;&#227;o da art&#233;ria radial direita para monitoriza&#231;&#227;o invasiva da press&#227;o arterial m&#233;dia e o implante de acesso venoso central. Recebeu alta da unidade de terapia intensiva no primeiro dia de p&#243;s-operat&#243;rio, em boas condi&#231;&#245;es cl&#237;nicas, em uso de antibioticoterapia profil&#225;tica com cefuroxima na dose de 750 mg tr&#234;s vezes por dia.</p>
    <p>No terceiro dia de p&#243;s-operat&#243;rio, come&#231;ou a apresentar distens&#227;o abdominal e no dia seguinte, calafrios e febre, sendo solicitadas hemoculturas. O acesso venoso central foi retirado, tendo sido iniciada antibioticoterapia emp&#237;rica com ciprofloxacino na dose de 400 mg por dia.</p>
    <p>Nas hemoculturas e no exame microbiol&#243;gico da ponta do cateter venoso central foi identificada <italic>Klebsiella pneumoniae</italic> resistente ao ciprofloxacino e sens&#237;vel ao imipenem, antibi&#243;tico este que passou a ser utilizado na dose de 2 g por dia, com melhora tanto cl&#237;nica como laboratorial.</p>
    <p>Foi solicitada ecodopplercardiografia transtor&#225;cica para investiga&#231;&#227;o de endocardite, em que foram observados fun&#231;&#227;o ventricular direita e fun&#231;&#227;o ventricular esquerda preservadas, refluxo valvar mitral e tric&#250;spide de grau discreto, e presen&#231;a de massa m&#243;vel em &#225;trio direito, sendo sugerida a realiza&#231;&#227;o de ecocardiografia transesof&#225;gica.</p>
    <p>Ao ecocardiograma transesof&#225;gico, foi visibilizada presen&#231;a de massa m&#243;vel, hiperecog&#234;nica, com movimenta&#231;&#227;o aleat&#243;ria, medindo aproximadamente 30 mm, localizada no &#225;trio direito, aderida &#224; v&#225;lvula de Eust&#225;quio, sugerindo vegeta&#231;&#227;o endoc&#225;rdica (<xref ref-type="fig" rid="figura1">fig. 1</xref>).</p>
    <fig id="figura1">
      <graphic xlink:href="1678-4170-abc-88-04-0e79-00025-gf01.jpg"/></fig>
    <p>O paciente apresentou melhora do quadro infeccioso, permanecendo afebril a partir do quinto dia do in&#237;cio do antibi&#243;tico, com melhora concomitante do hemograma.</p>
    <p>No vig&#233;simo sexto dia de terapia espec&#237;fica, o paciente foi submetido a ecocardiografia transesof&#225;gica de controle, sendo visibilizada a v&#225;lvula de Eust&#225;quio sem sinais de vegeta&#231;&#227;o. N&#227;o havia outras altera&#231;&#245;es ao ecocardiograma. O paciente apresentava-se afebril, com padr&#245;es laboratoriais n&#227;o compat&#237;veis com quadro infeccioso.</p>
    <p>Recebeu alta hospitalar ap&#243;s quatro semanas de antibioticoterapia, sem sinais cl&#237;nicos e laboratoriais de infec&#231;&#227;o em atividade (<xref ref-type="fig" rid="figura2">fig. 2</xref>).</p>
    <fig id="figura2">
      <graphic xlink:href="1678-4170-abc-88-04-0e79-00025-gf02.jpg"/></fig>
    <p>
      <bold>Discuss&#227;o</bold>
    </p>
    <p>A endocardite em v&#225;lvula de Eust&#225;quio, condi&#231;&#227;o rara e com poucos casos descritos na literatura<sup>1,3</sup>, geralmente &#233; associada a endocardite de valva tric&#250;spide<sup>4</sup>.</p>
    <p>O fator predisponente mais comum para essa condi&#231;&#227;o &#233; o uso de drogas injet&#225;veis, sendo tamb&#233;m relacionada ao uso de cateter venoso central e de marcapasso<sup>5,6</sup>. Em nosso caso, a endocardite em v&#225;lvula de Eust&#225;quio foi decorrente do uso de cateter venoso central implantado durante a revasculariza&#231;&#227;o cir&#250;rgica do mioc&#225;rdio.</p>
    <p>O pat&#243;geno mais freq&#252;entemente isolado nessa condi&#231;&#227;o &#233; o <italic>Staphylococcus aureus</italic><sup>5,7,8</sup>, n&#227;o havendo relato de <italic>Klebsiella pneumoniae</italic> como encontrado em nosso paciente.</p>
    <p>O diagn&#243;stico de endocardite em v&#225;lvula de Eust&#225;quio geralmente &#233; feito por meio de ecocardiografia transesof&#225;gica, que possibilita melhor visibiliza&#231;&#227;o dessa regi&#227;o, comparativamente &#224; ecocardiografia transtor&#225;cica. No entanto, a ecocardiografia transtor&#225;cica ainda &#233; o exame inicial de escolha, devendo a ecocardiografia transesof&#225;gica ser realizada diante da suspeita de vegeta&#231;&#227;o ao ecocardiograma transtor&#225;cico ou diante de quadro cl&#237;nico sugestivo de endocardite<sup>5,9,10</sup>.</p>
    <p>O tratamento para essa condi&#231;&#227;o inicialmente &#233; cl&#237;nico, com antibioticoterapia apropriada, sendo indicada cirurgia nos casos refrat&#225;rios ao tratamento. Em nosso paciente, houve remiss&#227;o do processo infeccioso ap&#243;s quatro semanas com antibioticoterapia espec&#237;fica, n&#227;o havendo necessidade de interven&#231;&#227;o cir&#250;rgica.</p>
    <p>
      <bold>Conclus&#227;o</bold>
    </p>
    <p>A endocardite em valva de Eust&#225;quio isoladamente &#233; uma possibilidade que deve ser investigada diante de suspeita cl&#237;nica em portadores de cateteres centrais.</p>
    <p>
      <fn id="back" fn-type="corresp">
        <label>
          <bold>Correspond&#234;ncia:</bold>
        </label>
        <p> Viviane Cordeiro Veiga </p>
        <p> Alameda Hungria, 89 </p>
        <p> 06474-140 &#150; Barueri, SP </p>
        <p> E-mail: </p>
        <p>
          <email xlink:href="vcveiga@cardiol.br">vcveiga@cardiol.br</email>
        </p>
      </fn>
    </p>
    <p>Artigo recebido em 19/05/06; revisado recebido em 16/08/06; aceito em 14/09/06.</p>
  </body>
  <back>
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  </back>
  <sub-article article-type="translation" id="TRen" xml:lang="en">
    <front-stub>
      <article-categories>
        <subj-group subj-group-type="heading">
          <subject>Case Report</subject>
        </subj-group>
      </article-categories>
      <title-group>
        <article-title xml:lang="en">Eustachian valve endocarditis</article-title>
      </title-group>
      <abstract xml:lang="en">
        <p>Eustachian valve endocarditis is a rare condition that affects mostly injectable drug users and patients using pacemakers or central venous catheter. We describe the case of a patient who underwent myocardial revascularization with extracorporeal circulation and who presented Eustachian valve endocarditis in the postoperative period, diagnosed by echocardiogram. The blood culture identified Klebsiella pneumoniae. He received appropriate antibiotic therapy and presented resolution of the condition within four weeks.</p>
      </abstract>
      <kwd-group xml:lang="en">
        <kwd>Endocarditis</kwd>
        <kwd>Eustachian valve</kwd>
        <kwd>heart valves</kwd>
      </kwd-group>
    </front-stub>
    <body>
      <p>
        <bold>CASE REPORT</bold>
      </p>
      <p>
        <bold>Eustachian valve endocarditis</bold>
      </p>
      <p>
        <bold>Viviane Cordeiro Veiga; Ana Cristina Carlo Magno Molinari; C&#237;ntia Mara Farias; Amilton Silva Junior; Elias C&#233;sar Hauy Marum; Salom&#243;n Ordinola Rojas; Marcelo Luiz Patr&#237;cio; Henry Abensur</bold>
      </p>
      <p>Real e Benem&#233;rita Associa&#231;&#227;o Portuguesa de Benefic&#234;ncia &#150; S&#227;o Paulo, SP, Brazil</p>
      <p>
        <xref ref-type="corresp" rid="back-body2">Mailing address</xref>
      </p>
      <p>
        <bold>ABSTRACT</bold>
      </p>
      <p>Eustachian valve endocarditis is a rare condition that affects mostly injectable drug users and patients using pacemakers or central venous catheter. We describe the case of a patient who underwent myocardial revascularization with extracorporeal circulation and who presented Eustachian valve endocarditis in the postoperative period, diagnosed by echocardiogram. The blood culture identified <italic>Klebsiella pneumoniae</italic>. He received appropriate antibiotic therapy and presented resolution of the condition within four weeks.</p>
      <p><bold>Key words:</bold> Endocarditis; Eustachian valve, heart valves.</p>
      <p>
        <bold>Introduction</bold>
      </p>
      <p>Eustachian valve endocarditis is a rare condition that affects mostly injectable drug users and patients using pacemakers or central venous catheter<sup>1,2</sup>.</p>
      <p>In fetal circulation, the Eustachian valve deviates blood from the inferior vena cava to the left atrium through the oval foramen.</p>
      <p>The objective of this study is to report a case of Eustachian valve endocarditis in the postoperative period of cardiac surgery.</p>
      <p>
        <bold>Case Report</bold>
      </p>
      <p>A 45-year-old male patient, with diagnosis of coronary insufficiency, who underwent myocardial revascularization with anastomosis from the right internal thoracic artery to the right coronary artery, as well as from the left radial artery to the left marginal branch, with extracorporeal circulation and no intercurrent events. The invasive procedures during surgery were mean arterial pressure and placement of a central venous catheter. The patient was discharged from the intensive care unit on the first postoperative day in good clinical conditions, on prophylactic antibiotic therapy with cefuroxime 750 mg, three times a day.</p>
      <p>On the third postoperative day, he presented abdominal bloating and on the next day, shivering and fever. Blood was withdrawn for culture, the central venous catheter was removed and the patient initiated on empirical antibiotic therapy with ciprofloxacin 400mg/day.</p>
      <p>The results of blood culture and microbiological examination of the central venous line tip was <italic>Klebsiella pneumoniae</italic> resistant to ciprofloxacin and sensitive to imipenem, which was prescribed at 2g/day, with clinical and laboratory improvement.</p>
      <p>A transthoracic Doppler echocardiogram was performed to investigate endocarditis and the following were observed: preserved right and left ventricular function, discreet mitral and tricuspid valve reflux and presence of a mobile mass on the right atrium.</p>
      <p>Therefore, a transesophageal echocardiogram was required and showed a mobile and hyperechogenic mass on the right atrium, with random movement and measuring approximately 30 mm, attached to the Eustachian valve, suggesting an endocardial vegetation (<xref ref-type="fig" rid="fig1-body2">Figure 1</xref>).</p>
      <fig id="fig1-body2">
        <graphic xlink:href="1678-4170-abc-88-04-0e79-00025-gf01-en.jpg"/></fig>
      <p>The infectious condition improved and the patient had no fever as of the 5<sup>th</sup> day on antibiotic, with simultaneous improvement in complete blood count.</p>
      <p>On day 26 of specific therapy, a control transesophageal echocardiogram was performed and the Eustachian valve was observed with no vegetation signs. No other alterations were found in the echocardiogram. The patient was afebrile and the laboratory test results were not compatible with an infectious condition.</p>
      <p>He was discharged after four-week antibiotic therapy, with no clinical or laboratory signs of infection (<xref ref-type="fig" rid="fig2-body2">Figure 2</xref>).</p>
      <fig id="fig2-body2">
        <graphic xlink:href="1678-4170-abc-88-04-0e79-00025-gf02-en.jpg"/></fig>
      <p>
        <bold>Discussion</bold>
      </p>
      <p>Eustachian valve endocarditis is a rare condition and there are few cases described in the literature<sup>1,3</sup>, which are usually associated with tricuspid valve endocarditis<sup>4</sup>.</p>
      <p>The most common predisposing factor for this disease is use of injectable drugs; it is also related to placement of central venous catheter and use of pacemakers<sup>5,6</sup>. In the case reported, Eustachian valve endocarditis resulted from a central venous catheter placed during a myocardial revascularization surgery.</p>
      <p>The agent more often isolated in this condition is <italic>Staphylococus aureus</italic> <sup>5,7,8</sup>, and there are no reports of <italic>Klebsiella pneumoniae</italic>, as observed in this patient.</p>
      <p>The diagnosis of Eustachian valve endocarditis is commonly made by means of transesophageal echocardiogram, which enables better visualization of the region as compared with transthoracic echocardiogram. Nevertheless, the latter remains the first choice exam; the transesophageal echocardiogram should be carried out if any vegetation is suspected on a transthoracic echocardiogram, or in case of a clinical picture suggesting endocarditis<sup>5,9,10</sup>.</p>
      <p>The initial treatment for this condition is clinical, with appropriate antibiotic therapy, and surgery is indicated in non-responsive cases. Our patient presented remission of the infectious process after four-week treatment with specific antibiotics and required no surgical intervention.</p>
      <p>
        <bold>Conclusion</bold>
      </p>
      <p>Isolated Eustachian valve endocarditis is a condition that should be investigated in case of clinical suspicion in patients using central venous catheters.</p>
      <p>
        <bold>References</bold>
      </p>
      <p>
        <fn id="back-body2" fn-type="corresp">
          <label>
            <bold>Mailing address:</bold>
          </label>
          <p> Viviane Cordeiro Veiga</p>
          <p> Alameda Hungria, 89</p>
          <p> 06474-140 &#150; Barueri, SP</p>
          <p> E-mail: </p>
          <p>
            <email xlink:href="vcveiga@cardiol.br">vcveiga@cardiol.br</email>
          </p>
        </fn>
      </p>
      <p>Manuscript received May 19, 2006; revised manuscript received August 16, 2006; Accepted September 14, 2006.</p>
    </body>
  </sub-article>
</article>
